Case Report
Traumatic bilateral atlantoaxial rotatory subluxation mimicking as torticollis in an adult female

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Abstract

Rotatory subluxation of the atlantoaxial joint in adults is a rare, but potentially life-threatening injury. Delayed or missed diagnosis can lead to catastrophic consequences. Early recognition and prompt treatment is paramount to avoid long-term morbidity and disability. We report on an instance of bilateral atlantoaxial rotatory subluxation (AARS) in a 25-year-old female who presented to the Casualty Department with a painful neck, right-sided hemiparesis and torticollis after a road traffic collision. Reduction was achieved by controlled cervical traction followed by immobilization in a four-post Halo brace, with complete resolution of her symptoms. At the 12-month follow-up, she had normal neck movements with no signs of instability.

Introduction

Atlantoaxial rotatory subluxation (AARS) is characterized by incomplete dislocation of the inferior atlantal and superior axial articular facets, and is usually reducible.1 Conservative treatment is usually successful, but occasionally may require open reduction if diagnosis is delayed.2 It is primarily seen in the pediatric population, and is rare in adults.3 Patients typically present with painful torticollis and a characteristic ‘cock robin’ position, with only few cases reported so far.3 Due to its rarity, it is usually overlooked, leading to incorrect diagnosis and management.4 The current case is a good example of post-traumatic AARS in an adult that was treated successfully by conservative means.

Section snippets

Case report

A 25-year-old female presented to the Casualty Department with painful torticollis after a road traffic collision. The car she was driving was hit side-on by an uncontrolled car that was travelling at 40 mph, which resulted in her car colliding with the central reservation. She was wearing a seatbelt and airbags were deployed. The patient presented with restricted and painful neck movements, along with a right-sided weakness. On examination, midline tenderness was present in the upper cervical

Discussion

AARS, also known as rotary dislocation, rotatory displacement, rotary deformity, rotational subluxation, rotary fixation and spontaneous hyperemic dislocation, is a rare injury.5, 6, 7 The atlanto-occipital joint is formed by long concave, elliptical superior facets of the C1 vertebra with convex occipital condyles. Because of the long anteroposterior axis of these joints, they provide approximately 20° to 30° of ‘nodding’.8 The atlantoaxial joint, on the other hand, is specifically designed

Conclusion

AARS is a rare injury in adults and can lead to a catastrophic clinical outcome if diagnosis is missed or delayed. A high index of suspicion with early involvement of a specialist is imperative for a successful outcome. Plain radiographs can be difficult to interpret, even by an experienced radiologist; hence, CT scanning with 3-D reconstruction should be the imaging modality of choice when there is clinical suspicion of AARS. The authors stress that AARS should always be included in the

References (10)

  • P. Missori et al.

    A C1–C2 locked facet in a child with atlantoaxial roratory fixation

    J Neurosurg (6 Suppl Pediatrics)

    (2005)
  • B.R. Subach et al.

    Current management of paediatric atlantoaxial rotatory subluxation

    Spine

    (1998)
  • R.N. Jones

    Rotatory dislocation of both atlanto-axial joints

    J Bone Joint Surg (Br)

    (1984)
  • S. Maile et al.

    Atlantoaxial rotatory subluxation: realignment and discharge within 48 h

    Eur J Emerg Med

    (2007)
  • M.B. Coutts

    Atlanto-epistropheal subluxations

    Arch Surg

    (1934)
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